Journal of Clinical Pediatrics ›› 2023, Vol. 41 ›› Issue (3): 192-196.doi: 10.12372/jcp.2023.21e1226
• Hematology and Oncology Disease • Previous Articles Next Articles
CHEN Yanfei, ZHONG Xuemei(), MA Xin, LIAO Weiwei, LIU Rong, ZOU Jizhen
Received:
2021-08-25
Published:
2023-03-15
Online:
2023-03-10
CHEN Yanfei, ZHONG Xuemei, MA Xin, LIAO Weiwei, LIU Rong, ZOU Jizhen. Clinical characteristics of intestinal thrombotic microangiopathosis associated with allogeneic hematopoietic stem cell transplantation in children[J].Journal of Clinical Pediatrics, 2023, 41(3): 192-196.
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病例 | 性别 | 年龄 | 诊 断 | 症 状 | 胃镜及结肠镜特点 | 病理特征 | 治 疗 | 转归 |
---|---|---|---|---|---|---|---|---|
1 | 女 | 2岁 | 先天性粒细胞缺乏 | 移植术后50天,稀便、血便(600 mL/d),顽固性休克,不易控制的高血压、浮肿、血尿、蛋白尿等 | 胃、十二指肠可见出血,末端回肠充血水肿,血管网消失。全大肠血管网消失,黏膜充血水肿、质脆、易出血。乙状结肠及直肠黏膜出血、水肿,局部黏膜脱落 | 末端回肠未见黏膜上皮及固有层;回盲部腺体不典型增生及缺失,末端回肠及横结肠可见微血栓形成及CMV包涵体 | 停CsA,加用MMF;多次CRRT,去纤苷 | 30天后逐渐临床好转 |
2 | 男 | 2岁5个月 | 尼曼匹克 病 | 移植术后26天稀便及血便(最大600~800 mL),皮肤改变 | 胃可见黏膜水肿及陈旧性出血,十二指肠未见异常。全大肠黏膜水肿、质脆、易出血 | 胃窦腺体不典型增生及腺体缺失,部分可见微血栓,结直肠腺体脱落。CMV(-),EB病毒(-) | 减少CsA,增加卢克替尼量 | 2周左右好转 |
3 | 女 | 8岁2个月 | 白血病 | 稀便伴血便(500~ 600 mL),皮疹 | 食管可见陈旧性出血。胃及十二指肠黏膜水肿及部分糜烂。 结直肠黏膜水肿、血管网消失,质脆、易出血 | 十二指肠腺体缺失,横结肠可见微血栓形成,CMV(-),EB病毒(-) | 换用MMF | 1周左右好转 |
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