Journal of Clinical Pediatrics ›› 2023, Vol. 41 ›› Issue (1): 60-65.doi: 10.12372/jcp.2023.22e0461
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XU Yongli, YANG Jing, ZHOU Lanqi, ZHOU Jianhua()
Received:
2022-04-18
Published:
2023-01-15
Online:
2023-02-16
Contact:
ZHOU Jianhua
E-mail:Jhzhou99@qq.com
XU Yongli, YANG Jing, ZHOU Lanqi, ZHOU Jianhua. 17q12 microdeletion syndrome: a report of three cases and literature review[J].Journal of Clinical Pediatrics, 2023, 41(1): 60-65.
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项 目 | 例1 | 例2 | 例3 |
---|---|---|---|
诊断年龄/岁 | 7 | 8 | 7 |
发病年龄/岁 | 4 | 8 | 7 |
性别 | 男 | 男 | 女 |
肾病家族史 | 无 | 无 | 无 |
蛋白尿 | 无 | ++ | + |
微量白蛋白/mg·L-1 | 2.6 | 710.5 | 189 |
24小时尿微量总蛋白/mg | 59.8 | 680 | 415.8 |
血肌酐/μmo1·L-1 | 40 | 41 | 271 |
尿酸/μmo1·L-1 | 646.0 | 583.0 | 493.0 |
丙氨酸转氨酶/U·L-1 | 21 | 164 | 17 |
天冬氨酸转氨酶/U·L-1 | 25 | 205 | 29 |
碱性磷酸酶/U·L-1 | 301 | 327 | 467 |
总胆固醇/mmol·L-1 | 3.30 | 8.15 | 6.5 |
血镁/mmol·L-1 | 0.56 | 0.46 | 1.03 |
糖尿病 | + | + | - |
肾脏大小/cm | 9.9×4.4(左) | 6.8×2.4(左) | 8.1×2.6(左) |
10.6×4.1(右) | 9.5×4.2(右) | 5.7×1.5(右) |
"
基 因 | 例1 | 例2 | 例3 | 显性遗传对应疾病 |
---|---|---|---|---|
CCL3、CCL4 | - | + | - | |
CCL4L2、CCL3L1、CCL3L3 | - | + | - | |
TBC1D3B/3C/3G/3H/3F | - | + | - | |
ZNHIT3 | - | - | - | |
MYO191) | - | - | - | 高钾性周期性麻痹 |
PIGW | - | - | - | |
GGNBP2 | - | - | - | |
DHRS11 | - | - | - | |
MRM1 | - | - | - | |
LHX11) | - | - | - | Mayer-Rokitansky-Kuster-Hauser 综合征、输尿管膨出、肾囊肿和糖尿病综合征 |
AATF | - | - | - | |
ACACA | - | - | - | |
C17orf78 | - | - | - | |
TADA2A | - | - | - | |
DUSP14 | - | - | - | |
SYNRG | - | - | - | |
DDX521) | - | - | - | Robinow 综合征、常染色体显性非综合征性智力障碍 |
HNF1B1) | - | - | - | 肾囊肿和糖尿病综合征 ( RCAD )、Hnf1b 相关的ADTKD 、 MODY5 等 |
YWHAEP7 | - | - | - | |
TBC1D31) | - | + | - | 前列腺癌 |
"
肾脏 | 多囊肾发育不良、慢性肾衰竭、蛋白尿、低镁血症、高尿酸血症皮质-髓质分化不良、肾积水或输尿管扩张、产前超声双侧高回声肾、马蹄形和重复肾、集合系统异常和双侧肾积水、 | |
---|---|---|
肝脏 | 肝功能异常、肝酶水平无症状升高(常见)、碱性磷酸酶(AP)升高、新生儿胆汁淤积症(罕见)、胆管稀少 | |
糖尿病 | 青年5型成熟型糖尿病(MODY5) | |
神经系统 | 神经发育或神经精神障碍(例如发育迟缓、自闭症谱系障碍、注意力缺陷/多动障碍、精神分裂症和双相情感障碍) | |
其他 | 胰腺结构性损伤 | 胰腺发育不全、胰体尾部发育不良伴头部轻度萎缩,可伴胰腺外分泌功能障碍 |
生殖系统 | MRKH综合征、双角子宫、双胎子宫、残缺子宫、双阴道、双侧或单侧隐睾 | |
面部畸形 | 眼睛畸形、斜视、高拱形眉毛、鼻梁塌陷 |
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